コーパス検索結果 (left1)
通し番号をクリックするとPubMedの該当ページを表示します
1 EDMD is also caused by X-linked recessive loss-of-functi
2 EDMD-linked genes were necessary for the initial separat
5 nclude Emery-Dreifuss muscular dystrophy (AD-EDMD) and Hutchinson-Gilford progeria, the premature agi
10 /C-mediated NMJ defects contribute to the AD-EDMD disease phenotype and provide insights into the cel
14 on cells from 10 patients diagnosed with an EDMD spectrum disease with different mutations in seven
16 f blood cells, which suggests that autosomal EDMD is not caused by indirect reduction of emerin level
17 1 and LAP2, suggesting Lmo7 activity is both EDMD-relevant and inhibited by direct binding to emerin.
19 n, but not emerin mutant P183H (which causes EDMD and selectively disrupts binding to Lmo7), decrease
22 tion of extended dynamic mode decomposition (EDMD) to uncover patterns relating to badger social orga
23 howed that the two nuclear envelope defects (EDMD LMNA, EDMD emerin) were highly related disorders an
24 tioselective desymmetrisation of meso-diols (EDMD) by small molecule catalysts has emerged as a power
29 linked to Emery-Dreifuss muscular dystrophy (EDMD) and centronuclear myopathy (CNM) in Drosophila and
30 dominant Emery-Dreifuss muscular dystrophy (EDMD) and related disorders with a predominant cardiomyo
32 lies with Emery-Dreifuss muscular dystrophy (EDMD) have been studied both by DNA sequencing and by em
37 ly proven Emery-Dreifuss muscular dystrophy (EDMD) who followed an unusual course and had uncommon cl
38 ated with Emery-Dreifuss muscular dystrophy (EDMD) with conduction defects and dilated cardiomyopathy
39 those of Emery-Dreifuss muscular dystrophy (EDMD), caused by mutations in A-type lamins (LMNA) and o
40 t include Emery-Dreifuss muscular dystrophy (EDMD), dilated cardiomyopathy (DCM), limb-girdle muscula
42 model of Emery-Dreifuss muscular dystrophy (EDMD), we show here that lamin A loss deregulated PcG po
49 of these, Emery-Dreifuss muscular dystrophy (EDMD-AD) and a form of dilated cardiomyopathy (CMD1A), i
50 dominant Emery-Dreifuss muscular dystrophy (EDMD-AD) and in dilated cardiomyopathy and conduction-sy
51 plate for establishing a biomarker panel for EDMD and direct further investigation into its pathomech
54 To identify disease-specific transcripts for EDMD, we applied a leave-one-out (LOO) cross-validation
56 upon the hypothesis that cardiac defects in EDMD are caused by absence of emerin from intercalated d
57 We observe that Net39 is downregulated in EDMD patients, implicating Net39 in the pathogenesis of
58 the nuclear envelope and Rb and MyoD fail in EDMD at the point of myoblast exit from the cell cycle,
59 sprin-2, telethonin, and FHL-2 identified in EDMD with DCM and hypertrophic cardiomyopathy patients.
67 the two nuclear envelope defects (EDMD LMNA, EDMD emerin) were highly related disorders and were also
68 conclude that Lmo7 positively regulates many EDMD-relevant genes (including emerin), and is feedback-
69 own as autosomal dominant Emery-Dreifuss MD (EDMD-AD) and dilated cardiomyopathy and conduction-syste
71 human LEM2 mutations as a potential cause of EDMD and further suggest human LEM2 mutations might caus
73 in complexes are discussed in the context of EDMD disease mechanisms and potential in vivo functions.
75 ecapitulated key skeletal muscle features of EDMD, including muscle wasting, impaired muscle contract
77 a direct contributor to the pathogenesis of EDMD that acts by protecting against mechanical stress a
80 ients with the autosomal dominant variant of EDMD, we examined the lamin A/C gene, identifying a de-n
82 sprin-2 (SYNE2) in 190 probands with EDMD or EDMD-like phenotypes identified four heterozygous missen
83 te-specific amino acid substitutions in PLD, EDMD-AD and CMD1A reveals distinct functional domains of
85 n of easily accessible catalysts used in the EDMD and compares their performance with the existing en
87 ized in Lmna mutant cells and also linked to EDMD and DCM, restored MKL1 nuclear translocation and re
91 ) and nesprin-2 (SYNE2) in 190 probands with EDMD or EDMD-like phenotypes identified four heterozygou
92 -linked Emery-Dreifuss muscular dystrophy (X-EDMD) is inherited through mutations in emerin, a nuclea
93 1, LAP2, RBL2) known to be misregulated in X-EDMD patients and emerin-null mice was confirmed by real